• LOGIN
Repository logo

BORIS Portal

Bern Open Repository and Information System

  • Publication
  • Projects
  • Funding
  • Research Data
  • Organizations
  • Researchers
  • LOGIN
Repository logo
Unibern.ch
  1. Home
  2. Publications
  3. 2024 update: European consensus statement on gene therapy for spinal muscular atrophy.
 

2024 update: European consensus statement on gene therapy for spinal muscular atrophy.

Options
  • Details
BORIS DOI
10.48350/197867
Date of Publication
July 2024
Publication Type
Article
Division/Institute

Universitätsklinik fü...

Author
Kirschner, Janbernd
Bernert, Günther
Butoianu, Nina
De Waele, Liesbeth
Fattal-Valevski, Aviva
Haberlova, Jana
Moreno, Teresa
Klein, Andrea Katharina
Universitätsklinik für Kinderheilkunde
Universitätsklinik für Kinderheilkunde, Neuropädiatrie
Kostera-Pruszczyk, Anna
Mercuri, Eugenio
Quijano-Roy, Susana
Sejersen, Thomas
Tizzano, Eduardo F
van der Pol, W Ludo
Wallace, Sean
Zafeiriou, Dimitrios
Ziegler, Andreas
Muntoni, Francesco
Servais, Laurent
Subject(s)

600 - Technology::610...

Series
European journal of paediatric neurology
ISSN or ISBN (if monograph)
1090-3798
Publisher
Elsevier
Language
English
Publisher DOI
10.1016/j.ejpn.2024.06.001
PubMed ID
38878702
Uncontrolled Keywords

Adeno-associated vira...

Description
Spinal muscular atrophy (SMA) is one of the most common genetic diseases and was, until recently, a leading genetic cause of infant mortality. Three disease-modifying treatments have dramatically changed the disease trajectories and outcome for severely affected infants (SMA type 1), especially when initiated in the presymptomatic phase. One of these treatments is the adeno-associated viral vector 9 (AAV9) based gene therapy onasemnogene abeparvovec (Zolgensma®), which is delivered systemically and has been approved by the European Medicine Agency for SMA patients with up to three copies of the SMN2 gene or with the clinical presentation of SMA type 1. While this broad indication provides flexibility in patient selection, it also raises concerns about the risk-benefit ratio for patients with limited or no evidence supporting treatment. In 2020, we convened a European neuromuscular expert working group to support the rational use of onasemnogene abeparvovec, employing a modified Delphi methodology. After three years, we have assembled a similar yet larger group of European experts who assessed the emerging evidence of onasemnogene abeparvovec's role in treating older and heavier SMA patients, integrating insights from recent clinical trials and real-world evidence. This effort resulted in 12 consensus statements, with strong consensus achieved on 9 and consensus on the remaining 3, reflecting the evolving role of onasemnogene abeparvovec in treating SMA.
Handle
https://boris-portal.unibe.ch/handle/20.500.12422/178202
Show full item
File(s)
FileFile TypeFormatSizeLicensePublisher/Copright statementContent
1-s2.0-S1090379824000874-main.pdftextAdobe PDF453.03 KBAttribution (CC BY 4.0)publishedOpen
BORIS Portal
Bern Open Repository and Information System
Build: d1c7f7 [27.06. 13:56]
Explore
  • Projects
  • Funding
  • Publications
  • Research Data
  • Organizations
  • Researchers
More
  • About BORIS Portal
  • Send Feedback
  • Cookie settings
  • Service Policy
Follow us on
  • Mastodon
  • YouTube
  • LinkedIn
UniBe logo